Browse > Article
http://dx.doi.org/10.3340/jkns.2011.50.2.139

Cervical Fibrous Dysplasia Presenting as a Pathologic Fracture in an Older Patient  

Lee, Su-Heon (Department of Neurosurgery & Medical Research Institute, Pusan National University Hospital, Pusan National University School of Medicine)
Han, In-Ho (Department of Neurosurgery & Medical Research Institute, Pusan National University Hospital, Pusan National University School of Medicine)
Kang, Dong-Wan (Department of Neurosurgery & Medical Research Institute, Pusan National University Hospital, Pusan National University School of Medicine)
Choi, Byung-Kwan (Department of Neurosurgery & Medical Research Institute, Pusan National University Hospital, Pusan National University School of Medicine)
Publication Information
Journal of Korean Neurosurgical Society / v.50, no.2, 2011 , pp. 139-142 More about this Journal
Abstract
Vertebral involvement of fibrous dysplasia (FD) is rare, especially in the cervical spine. Moreover, cervical FD presenting as a pathologic fracture in older patients is extremely rare. We report a case of symptomatic cervical FD associated with pathologic fracture in a 63-year-old man. The patient presented with progressive weakness of the left arm and pain in the shoulder and arm. Radiologic studies revealed a collapsed and typical 'ground glass' radiolucency of C4. Multiple lytic lesions involved the odontoid process of C2 and the body, left pedicle, and posterior elements of C4. Combined anterior and posterior decompression and reconstruction were performed. Post-operatively, the histopathologic examination confirmed FD. On the post-operative follow-up examination, the neurologic deficits had completely resolved.
Keywords
Fibrous dysplasia; Cervical spine; Elderly;
Citations & Related Records

Times Cited By Web Of Science : 0  (Related Records In Web of Science)
Times Cited By SCOPUS : 0
연도 인용수 순위
  • Reference
1 Albright F, Butler AM, Hampton AO, Smith P : Syndrome characterized by osteitis fibrosa disseminata, area of pigmentation and endocrine dysfunction, with precocious puberty in females. N Engl J Med 216 : 726-746, 1937
2 Arantes M, Vaz AR, Honavar M, Resende M, Pereira JR : Fibrous dysplasia of the first cervical vertebra. Spine 33 : E933-E935, 2008   DOI   ScienceOn
3 Dang D, Baig MN, Christoforidis G, Chiocca EA, Gabriel J : C2/C3 pathologic fractures from polyostotic fibrous dysplasia of the cervical spine treated with percutaneous vertebroplasty. Eur Spine J 16 Suppl 3 : 250-254, 2007   DOI
4 DiCaprio MR, Enneking WF : Fibrous dysplasia. Pathophysiology, evaluation, and treatment. J Bone Joint Surg Am 87 : 1848-1864, 2005   DOI   ScienceOn
5 Dickerman RD : Severe fibrous dysplasia of the craniovertebral junction with transient quadriparesis : a complicated case. Br J Neurosurg 19 : 495, 2005   DOI   ScienceOn
6 Green GS : Polyostotic fibrous dysplasia. Clin Nucl Med 9 : 600-602, 1984   DOI
7 Leet AI, Chebli C, Kushner H, Chen CC, Kelly MH, Brillante BA, et al. : Fracture incidence in polyostotic fibrous dysplasia and the McCune-Albright syndrome. J Bone Miner Res 19 : 571-577, 2004
8 Lichtenstein L : Polyostotic fibrous dysplasia. Arch Surg 36 : 874-898, 1938   DOI
9 Marshman LA, David KM, O'Donovan DG, Chawda SJ : Fibrous dysplasia of the cervical spine presenting as a pathological fracture. Br J Neurosurg 18 : 527-533, 2004   DOI   ScienceOn
10 Medow JE, Agrawal BM, Resnick DK : Polyostotic fibrous dysplasia of the cervical spine : case report and review of the literature. Spine J 7 : 712-715, 2007   DOI   ScienceOn
11 Peltier J, Lefranc M, Fichten A, Cordonnier C, Toussaint P, Desenclos C, et al. : Odontoid fracture complicating Jaffe-Lichtenstein disease. Case report. J Neurosurg Spine 8 : 295-299, 2008   DOI   ScienceOn
12 Proschek D, Orler R, Stauffer E, Heini P : Monostotic fibrous dysplasia of the spine : report of a case involving a cervical vertebra. Arch Orthop Trauma Surg 127 : 75-79, 2007   DOI   ScienceOn
13 Stompro BE, Alksne JF, Press GA : Diagnosis and treatment of an odontoid fracture in a patient with polyostotic fibrous dysplasia : case report. Neurosurgery 24 : 905-909, 1989   DOI
14 Villas C, Martinez-Peric R : Monostotic fibrous dysplasia of a cervical vertebra. Eur Spine J 1 : 137-139, 1992   DOI   ScienceOn