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http://dx.doi.org/10.3348/kjr.2013.14.6.946

A Case of an Idiopathic Massive Osteolysis with Skip Lesions  

Ozbayrak, Mustafa (Department of Radiology, Arnavutkoy State Hospital)
Yilmaz, Mehmet Halit (Department of Radiology, Cerrahpasa Medical Faculty, Istanbul University)
Kantarci, Fatih (Department of Radiology, Cerrahpasa Medical Faculty, Istanbul University)
Ozer, Harun (Department of Radiology, Cerrahpasa Medical Faculty, Istanbul University)
Harmanci, Kemal (Department of Radiology, Cerrahpasa Medical Faculty, Istanbul University)
Babacan, Muharrem (Department of Orthopedic Surgery, Cerrahpasa Medical Faculty, Istanbul University)
Dervisoglu, Sergulen (Department of Pathology, Cerrahpasa Medical Faculty, Istanbul University)
Publication Information
Korean Journal of Radiology / v.14, no.6, 2013 , pp. 946-950 More about this Journal
Abstract
A patient with a 2-year history of pain in the left arm, and decreased strengths unrelieved by non-steroidal anti-inflammatory therapy, was being referred for repeating radiography. The radiologic examinations have demonstrated a unique pattern of non-contiguous osteolysis in the left elbow, proximal and distal radius, ulna, wrist, carpal bones, proximal and distal metacarpals and phalanges. Multi-site biopsies were being performed and confirmed the diagnosis of massive osteolysis. To our knowledge, this is the first case in which multifocal, non-contiguous osteolysis with skip lesions without associated nephropathy and without a hereditary pattern is being described in one extremity.
Keywords
Idiopathic osteolysis; Gorham-Stout syndrome; Disappearing bone disease;
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1 Jackson JBS. A boneless arm. Boston Med Surg J 1838;18:368-369   DOI
2 Jackson JBS. Absorption of the humerus after fracture. Boston Med Surg J 1872;10:245-247
3 Gorham LW, Stout AP. Massive osteolysis (acute spontaneous absorption of bone, phantom bone, disappearing bone); its relation to hemangiomatosis. J Bone Joint Surg Am 1955;37-A:985-1004
4 Hardegger F, Simpson LA, Segmueller G. The syndrome of idiopathic osteolysis. Classification, review, and case report. J Bone Joint Surg Br 1985;67:88-93
5 Yoo SY, Hong SH, Chung HW, Choi JA, Kim CJ, Kang HS. MRI of Gorham's disease: findings in two cases. Skeletal Radiol 2002;31:301-306   DOI   ScienceOn
6 Sato K, Sugiura H, Yamamura S, Mieno T, Nagasaka T, Nakashima N. Gorham massive osteolysis. Arch Orthop Trauma Surg 1997;116:510-513   DOI
7 Resnick D, Kransdorf MJ. Bone and joint imaging, 3rd ed. Philadelphia: Elsevier Saunders, 2005:1449-1451
8 White AA 3rd. Disappearing bone disease with arthropathy and severe scarring of the skin. A report of four cases seen in South Vietnam. J Bone Joint Surg Br 1971;53:303-309   DOI
9 Beals RK, Bird CB. Carpal and tarsal osteolysis. A case report and review of the literature. J Bone Joint Surg Am 1975;57:681-686   DOI
10 Tookman AG, Paice EW, White AG. Idiopathic multicentric osteolysis with acro-osteolysis. A case report. J Bone Joint Surg Br 1985;67:86-88
11 Tauro B. Multicentric Gorham's disease. J Bone Joint Surg Br 1992;74:928-929
12 Downing ND, Garnavos C, Lunn PG. Idiopathic multicentric osteolysis principally affecting the phalanges of the hands and feet. J Hand Surg Br 1996;21:656-659   DOI   ScienceOn
13 Burkhard O, Beyer J, Schrezenmeir J, Brunier A, Delling G. [A case of idiopathic multicentric osteolysis]. Med Klin (Munich) 1989;84:364-368
14 Johnson PM, McClure JG. Observations on massive osteolysis; a review of the literature and report of a case. Radiology 1958;71:28-42   DOI