Browse > Article
http://dx.doi.org/10.3345/kjp.2010.53.1.97

Macroglossia secondary to lymphangioma of the deep neck space: Report of two cases  

Cho, Han-Gil (Departments of Pediatrics, College of Medicine, Chonnam National University)
Kim, Soo-Young (Departments of Pediatrics, College of Medicine, Chonnam National University)
Song, Eun-Song (Departments of Pediatrics, College of Medicine, Chonnam National University)
Lee, Joon-Kyoo (Otolaryngology-Head and Neck Surgery, College of Medicine, Chonnam National University)
Choi, Young-Youn (Departments of Pediatrics, College of Medicine, Chonnam National University)
Publication Information
Clinical and Experimental Pediatrics / v.53, no.1, 2010 , pp. 97-102 More about this Journal
Abstract
Lymphangioma is a rare, benign, and hamartomatous tumor of the lymphatic vessels that shows a marked predilection for the head and neck region. When this tumor occurs on the tongue or mouth floor or in the deep neck space, blockage of the efferent lymphatic vessels can result in secondary macroglossia. We report here two patients who showed unusual macroglossia from birth. Initially, there was no noticeable cervical or mandibular swelling. However, mandibular swellings were noted during follow-up examinations, which led to MRI scans on the two infant patients at 5 months and 5 weeks of age, respectively. Subsequently, both patients were diagnosed with lymphangioma or lymphangiohemangioma in the deep neck space.
Keywords
Macroglossia; Lymphangioma; Cervical;
Citations & Related Records
연도 인용수 순위
  • Reference
1 Seashore JH, Gardiner LJ, Ariyan S. Management of giant cystic hygromas in infants. Am J Surg 1985;149:459-65   DOI   ScienceOn
2 Hartl DM, Roger G, Denoyelle F, Nicollas R, Triglia JM, Garabedian EN. Extensive lymphangioma presenting with upper airway obstruction. Arch Otolaryngol Head Neck Surg 2000;126:1378-82   PUBMED   ScienceOn
3 Stewart RE, Boggs W. Pathology of soft tissues and jaws. In : Stewart RE, Barber TK, Troutman KC, Wei SHY, editors. Pediatric dentistry. St. Louis : CV Mosby Co, 1982:184
4 Shafer WG, Hine MK, Levy BM. Developmental disturbances of the tongue. A textbook of oral pathology. 4th ed. Philadelphia : WB Saunders Co, 1983:24-5
5 Regezi JA, Sciubba JJ. Oral pathology. Clinical pathologic correlations. 2nd ed. Philadelphia : WB Saunders Co, 1993: 214-6
6 Padwa BL, Hayward PG, Ferraro NF, Mulliken JB. Cervicofacial lymphatic malformation: clinical course, surgical intervention and pathogenesis of skeletal hypertrophy. Plast Reconstr Surg 1995;95:951-60   DOI   ScienceOn
7 Lalwani AK, Engel TL. Teratoma of the tongue: a case report and review of the literature. Int J Pediatr Otorhinolaryngol 1992;24:261-8   DOI   ScienceOn
8 Brightman VJ. Diseases of the tongue. In : Lynch HA, editor. Burket's oral medicine. 9th ed. Philadelphia : Lippincott-Raven, 1994:251-7
9 Cable BB, Mair EA. Radiofrequency ablation of lymphagiomatous macroglossia. Laryngoscope 2001;111:1859-61   DOI   ScienceOn
10 Neville BW, Damm DD, Allen CM, Bouquot JE. Oral and maxillofacial pathology. 1st ed. Philadelphia : WB Saunders Co, 1995:395-7
11 Leboulanger N, Roger G, Caze A, Enjolras O, Denoyelle F, Garabedian EN. Utility of radiofrequency ablation for haemorrhagic lingual lymphangioma. Int J Pediatr Otorhinolaryngol 2008;72:953-8   DOI   ScienceOn
12 Lobitz B, Lang T. Lymphangioma of the tongue. Pediatr Emerg Care 1995;11:183-5   DOI   ScienceOn
13 Paladini D, Morra T, Guida F, Lamberti A, Martinelli P. Prenatal diagnosis and perniatal management of a lingual lymphangioma. Ultrasound Obstet Gynecol 1998;11:141-3   DOI   ScienceOn
14 Regezi JA, Scjubba JJ. Oral Pathology. Clinical pathologic correlations. 3rd ed. Philadelphia : WB Saunders Co, 1999:196-7
15 Rice JP, Carson SH. A case report of lingual lymphangioma presenting as recurrent massive tongue enlargement. Clin Pediatr (Phila)1985;24:47-50   DOI   ScienceOn
16 Heether J, Whalen T, Doolin E. Follow-up of complex unresectable lymphangiomas. Am Surg 1994;60:840-1   PUBMED
17 Deitmer T. Therapy of cystic lymphangioma in childhood. Report of 4 cases with manifestations in the area of the head-neck. Laryngorhinootologie 1996;75:166-70   DOI   PUBMED   ScienceOn
18 Kennedy TL. Cystic hygroma-lymphangioma: a rare and still unclear entity. Laryngoscope 1989;99(10 Pt 2 Suppl 49):1-10   PUBMED   ScienceOn
19 White MA. Lymphangioma of the tongue: report of a case. ASDC J Dent Child 1987;54:280-2   PUBMED   ScienceOn