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http://dx.doi.org/10.3904/kjm.2014.87.1.120

A Case of Diffuse Idiopathic Skeletal Hyperostosis Presenting with Dysphagia Secondary to Cervical Osteophyte and Restrictive Ventilatory Impairment  

Lee, Hong Jik (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Lee, Ji Hyun (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Kim, Min Jeong (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Byun, Ki Sup (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Yeo, Hyun Jung (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Im, Ho Joon (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Nam, Kyoung Sik (Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center)
Publication Information
The Korean Journal of Medicine / v.87, no.1, 2014 , pp. 120-125 More about this Journal
Abstract
Diffuse idiopathic skeletal hyperostosis (DISH) is a condition characterized by the calcification and ossification of soft tissue, and can lead to severe cervical kyphosis, presenting with a spectrum of physical complaints including dysphagia, hoarseness, stridor, aspiration pneumonia, and dyspnea due to airway compromise. Restrictive ventilatory impairment is very rare. We encountered a 73-year-old man with DISH presenting with progressive dysphagia and dyspnea over a few months. The symptoms were evaluated with a video fluoroscopy swallowing study and pulmonary function tests (PFT). The PFT revealed restrictive ventilatory impairment. A neck magnetic resonance imaging (MRI) study showed anterior cervical osteophytes causing upper airway compromise and compression of the esophagus. Osteophytes were removed surgically and the patient improved clinically. Here, we describe the case with a literature review.
Keywords
Diffuse idiopathic skeletal hyperostosis; Dysphagia; Osteophyte; Cervical; Restrictive ventilatory impairment;
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Times Cited By KSCI : 2  (Citation Analysis)
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