Journal of the Korean Association of Oral and Maxillofacial Surgeons

The Korean Association of Oral and Maxillofacial Surgeons (대한구강악안면외과학회)
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Sclerosing polycystic adenosis arising in the parotid gland with trismus: a case report and literature review

  • Yee, Young-Jae (Department of Oral and Maxillofacial surgery, Oral Science Research Center, Yonsei University College of Dentistry) ;
  • Han, Dawool (Department of Oral Pathology, Oral Cancer Research Institute, Yonsei University College of Dentistry) ;
  • Lee, Chena (Department of Oral and Maxillofacial Radiology, Yonsei University College of Dentistry) ;
  • Kim, Jun-Young (Department of Oral and Maxillofacial surgery, Oral Science Research Center, Yonsei University College of Dentistry)
  • Received : 2021.11.08
  • Accepted : 2022.01.03
  • Published : 2022.08.31
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Abstract

Sclerosing polycystic adenosis (SPA) is a rare, asymptomatic disease that occurs mainly in the salivary glands. We report the case of a 51-year-old man who presented with trismus and pain upon mouth opening. Magnetic resonance imaging revealed a 2-cm mass located in the anterior portion of the left parotid gland. SPA was diagnosed based on histopathological examination of the surgical specimen. In pathologic findings, there was a well-circumscribed multicystic nodule in the parenchyma. Dense fibrosis and chronic non-specific inflammatory cells were observed in the stroma. In 13 previous reports on SPA, the most preferred treatment was superficial or total parotidectomy. This report suggests that simple excision of SPA preserves facial nerve function and facial volume.

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References

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