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http://dx.doi.org/10.5125/jkaoms.2022.48.4.237

Sclerosing polycystic adenosis arising in the parotid gland with trismus: a case report and literature review  

Yee, Young-Jae (Department of Oral and Maxillofacial surgery, Oral Science Research Center, Yonsei University College of Dentistry)
Han, Dawool (Department of Oral Pathology, Oral Cancer Research Institute, Yonsei University College of Dentistry)
Lee, Chena (Department of Oral and Maxillofacial Radiology, Yonsei University College of Dentistry)
Kim, Jun-Young (Department of Oral and Maxillofacial surgery, Oral Science Research Center, Yonsei University College of Dentistry)
Publication Information
Journal of the Korean Association of Oral and Maxillofacial Surgeons / v.48, no.4, 2022 , pp. 237-241 More about this Journal
Abstract
Sclerosing polycystic adenosis (SPA) is a rare, asymptomatic disease that occurs mainly in the salivary glands. We report the case of a 51-year-old man who presented with trismus and pain upon mouth opening. Magnetic resonance imaging revealed a 2-cm mass located in the anterior portion of the left parotid gland. SPA was diagnosed based on histopathological examination of the surgical specimen. In pathologic findings, there was a well-circumscribed multicystic nodule in the parenchyma. Dense fibrosis and chronic non-specific inflammatory cells were observed in the stroma. In 13 previous reports on SPA, the most preferred treatment was superficial or total parotidectomy. This report suggests that simple excision of SPA preserves facial nerve function and facial volume.
Keywords
Neoplasm; Benign neoplasm; Tumor; Parotid gland; Trismus;
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