Pediatric Gastroenterology, Hepatology & Nutrition

  • 제22권6호
  • /
  • Pages.601-607
  • /
  • 2019
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  • 2234-8646(pISSN)
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  • 2234-8840(eISSN)
대한소아소화기영양학회 (The Korean Society of Pediatric Gastroenterology, Hepatology and Nutrition)
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Endoscopic Management of Pancreaticopleural Fistula in a Child with Hereditary Pancreatitis

  • Lee, Dahye (Department of Pediatrics, Seoul National University College of Medicine) ;
  • Lee, Eun Joo (Department of Pediatrics, Seoul National University College of Medicine) ;
  • Kim, Ju Whi (Department of Pediatrics, Seoul National University College of Medicine) ;
  • Moon, Jin Soo (Department of Pediatrics, Seoul National University College of Medicine) ;
  • Kim, Yong-Tae (Department of Internal Medicine, Seoul National University College of Medicine) ;
  • Ko, Jae Sung (Department of Pediatrics, Seoul National University College of Medicine)
  • 투고 : 2018.08.31
  • 심사 : 2018.09.29
  • 발행 : 2019.11.15
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초록

Pancreaticopleural fistula (PPF) a fistulous connection between the pancreas and pleural space due to prolonged chronic pancreatitis (CP). PPF is a very rare complication which presents in 0.4% of chronic pancreatitis cases, especially among children. We report a case involving a 3-year-old boy who presented with pleural effusion caused by a PPF, a complication of hereditary pancreatitis, which was, for the first time in Korea, successfully managed with endoscopic treatment. Chest radiography and computed tomography showed massive pleural effusion. Percutaneous catheter drainage was performed. High amylase levels were observed in the pleural fluid and serum, suggesting PPF. The patient was managed with bowel rest and octreotide infusion. Endoscopic retrograde cholangiopancreatography revealed CP, and pleural effusion was successfully managed with stent placement. PRSS1 genetic screening revealed R122H mutation.

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참고문헌

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피인용 문헌

  1. Endoscopic retrograde cholangiopancreatography in the treatment of pancreaticopleural fistula in children vol.26, pp.37, 2020, https://doi.org/10.3748/wjg.v26.i37.5718
  2. Pancreaticopleural fistula in children with chronic pancreatitis: a case report and literature review vol.20, pp.1, 2019, https://doi.org/10.1186/s12887-020-02174-x
  3. Pancreaticopleural fistula in a child with chronic pancreatitis harboring compound SPINK1 variants vol.21, pp.1, 2019, https://doi.org/10.1186/s12876-021-01842-1