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성인 십이지장-십이지장 장중첩증 및 재발성 췌장염과 관련된 관강내 십이지장 게실의 영상 소견: 증례 보고

Imaging Findings of an Intraluminal Duodenal Diverticulum Associated with Adult Duodeno-Duodenal Intussusception and Recurrent Pancreatitis: A Case Report

  • 이가영 (이화여자대학교 의과대학 이대목동병원 영상의학과) ;
  • 이정경 (이화여자대학교 의과대학 이대목동병원 영상의학과) ;
  • 이희성 (이화여자대학교 의과대학 이대목동병원 외과) ;
  • 이선영 (이화여자대학교 의과대학 이대목동병원 소화기내과) ;
  • 박상희 (이화여자대학교 의과대학 이대목동병원 병리과)
  • Ga Young Yi (Department of Radiology, Ewha Womans University, Mokdong Hospital) ;
  • Jeong Kyong Lee (Department of Radiology, Ewha Womans University, Mokdong Hospital) ;
  • Huisong Lee (Department of Surgery, Ewha Womans University, Mokdong Hospital) ;
  • Sun Young Yi (Department of Gastroenterology, Ewha Womans University, Mokdong Hospital) ;
  • SangHui Park (Department of Pathology, College of Medicine, Ewha Womans University, Mokdong Hospital)
  • 투고 : 2021.03.05
  • 심사 : 2021.07.17
  • 발행 : 2022.05.01

초록

관강내 십이지장 게실은 드문 선천성 이상으로, 십이지장 점막으로 구성된 낭성 병변이며, 위장 출혈, 십이지장 폐색 또는 췌장염과 함께 나타날 수 있다. 이 논문에서는 25세 성인 여성에서 십이지장-십이지장 장중첩증과 재발성 췌장염의 합병증을 일으킨 드문 관강내 십이지장 게실의 사례를 보고하는 바이다. CT, MRI, 상부위장관조영술등의 영상 검사에서 십이지장의 중복낭을 의심하였으나, 수술로 절제된 조직에서 병리학적으로 고유근육층이 없는 관강내 십이지장 게실로 확진되었다.

Intraluminal duodenal diverticulum (IDD) is a rare congenital abnormality, consisting of a saclike mucosal lesion in the duodenum. Cases of IDD can present with gastrointestinal bleeding, duodenal obstruction, or pancreatitis. Here, we report a rare case of a 25-year-old female presenting with IDD complicated by duodeno-duodenal intussusception and recurrent pancreatitis. The diagnosis was based on findings from radiologic examinations (CT and MRI), upper gastrointestinal series (barium swallow), and gastroduodenofiberscopy. Laparoscopic excision of the presumed duodenal duplication was performed. The subsequent histopathologic evaluation of the excised sac revealed normal mucosa on both sides, but the absence of a proper muscle layer confirmed the diagnosis of IDD. Radiologic detection of a saccular structure in the second portion of the duodenum can indicate IDD with duodeno-duodenal intussusception as the lead point.

키워드

참고문헌

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