Archives of Craniofacial Surgery (대한두개안면성형외과학회지)

Korean Cleft Palate-Craniofacial Association (대한두개안면성형외과학회)
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Reconstructive rhinoplasty with costal cartilage grafting: A case report of relapsing polychondritis

  • Lee, Yunhae (Department of Plastic and Reconstructive Surgery, Konkuk University Medical Center) ;
  • Choi, Hyungon (Department of Plastic and Reconstructive Surgery, Konkuk University Medical Center)
  • Received : 2019.09.03
  • Accepted : 2019.10.02
  • Published : 2019.10.20
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Abstract

Relapsing polychondritis (RP) is a rare autoimmune disorder of unknown etiology characterized by recurrent episodes of inflammation and the destruction of cartilaginous tissues, primarily involving the ear, nose, and the respiratory tract. Nasal chondritis is present in 24% of patients at the time of diagnosis and develops subsequently in 53% throughout the diseases progress. Progressive destruction of nasal cartilage leads to the characteristic flattening of the nasal bridge, resulting in the saddle nose deformity. In patients with RP, surgical management for saddle nose is carefully decided due to the disease relapsing characteristics. We present a RP patient with a saddle nose deformity who underwent reconstruction rhinoplasty with autologous costal cartilage grafting. At 6-month follow-up, the patient retained good esthetic results and showed neither complication nor relapse of RP.

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References

  1. Borgia F, Giuffrida R, Guarneri F, Cannavo SP. Relapsing polychondritis: an updated review. Biomedicines 2018;6:E84. https://doi.org/10.3390/biomedicines6030084
  2. Haug MD, Witt P, Kalbermatten FD, Rieger UM, Schaefer DJ, Pierer G. Severe respiratory dysfunction in a patient with relapsing polychondritis: should we treat the saddle nose deformity? J Plast Reconstr Aesthet Surg 2009;62:e7-10. https://doi.org/10.1016/j.bjps.2008.05.012
  3. McAdam LP, O'Hanlan MA, Bluestone R, Pearson CM. Relapsing polychondritis: prospective study of 23 patients and a review of the literature. Medicine (Baltimore) 1976;55:193-215. https://doi.org/10.1097/00005792-197605000-00001
  4. Damiani JM, Levine HL. Relapsing polychondritis: report of ten cases. Laryngoscope 1979;89(6 Pt 1):929-46. https://doi.org/10.1288/00005537-197906000-00009
  5. Isaak BL, Liesegang TJ, Michet CJ Jr. Ocular and systemic findings in relapsing polychondritis. Ophthalmology 1986;93:681-9. https://doi.org/10.1016/S0161-6420(86)33695-9
  6. Gubbels SP, Barkhuizen A, Hwang PH. Head and neck manifestations of Wegener's granulomatosis. Otolaryngol Clin North Am 2003;36:685-705. https://doi.org/10.1016/S0030-6665(03)00023-9
  7. Tobisawa Y, Shibata M. A case of saddle nose deformity caused by relapsing polychondritis: a long-term follow-up report after iliac bone grafting. J Plast Reconstr Aesthet Surg 2013;66:1621-2. https://doi.org/10.1016/j.bjps.2013.05.013
  8. Bell D, Wright D, Witt PD. Durability of nasal reconstruction in an adolescent with relapsing polychondritis treated with infliximab. Plast Reconstr Surg 2007;120:1087-8. https://doi.org/10.1097/01.prs.0000278184.60488.8e
  9. Jones FR. Relapsing polychondritis: case report. Plast Reconstr Surg 1973;51:331-3. https://doi.org/10.1097/00006534-197303000-00020
  10. Torossian JM, Dumas V, Allias F, Ninet J, Beziat JL. Nasal involvement in atrophic polychondritis: a case report. Ann Chir Plast Esthet 1999;44:262-5.
  11. Sajjadian A, Rubinstein R, Naghshineh N. Current status of grafts and implants in rhinoplasty: part I. Autologous grafts. Plast Reconstr Surg 2010;125:40e-49e. https://doi.org/10.1097/PRS.0b013e3181c82f12
  12. Maciazek-Chyra B, Szmyrka M, Skoczynska M, Sokolik R, Lasocka J, Wiland P. Relapsing polychondritis: analysis of symptoms and criteria. Reumatologia 2019;57:8-18. https://doi.org/10.5114/reum.2019.83234