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A Thoracolumbar Pure Spinal Epidural Cavernous Hemangioma - A Case Report -

흉요추부에서 발견된 경막외 해면상 혈관종 - 증례 보고 -

  • Choi, Byeong Sam (Department of Neurosurgery, Inje University Haeundae Paik Hospital) ;
  • Kim, Ju Yeon (Department of Pathology, Inje University Haeundae Paik Hospital) ;
  • Lee, Sungjoon (Department of Neurosurgery, Inje University Haeundae Paik Hospital)
  • 최병삼 (해운대백병원 신경외과학교실) ;
  • 김주연 (해운대백병원 병리과학교실) ;
  • 이승준 (해운대백병원 신경외과학교실)
  • Received : 2018.04.24
  • Accepted : 2018.10.08
  • Published : 2018.12.30

Abstract

Study Design: Case report. Objectives: We report a case of pure epidural cavernous hemangioma located at the thoracolumbar spine in a 53-year-old woman that mimicked a neurogenic tumor on magnetic resonance imaging (MRI). Summary of Literature Review: A pure spinal epidural cavernous hemangioma without bony involvement is a very rare lesion about which limited information is available in the literature. Materials and Methods: A 53-year-old woman visited our clinic for hypoesthesia with a tingling sensation in the left anterolateral thigh that had begun a month ago. No other neurologic symptoms or signs were present upon a neurologic examination. MRI from an outside hospital showed a $2.0{\times}0.5cm$ elongated mass at the T11-12 left neural foramen. The tumor was completely removed in piecemeal fashion. Results: The histopathologic examination revealed a cavernous hemangioma, which was the final diagnosis. The outcome was favorable in that only operation-related mild back pain remained, without any neurologic deficits, after a postoperative follow-up of 2 years and 3 months. No recurrence was observed on MRI at 2 years postoperatively. Conclusion: Pure epidural spinal cavernous hemangioma is very rare, and it is very difficult to differentiate from other epidural lesions. However, we believe that it should be included in the differential diagnosis of spinal epidural tumors due to its favorable prognosis.

연구계획: 증례 보고 목적: 신경인성 종양과 유사한 흉요추부의 경막외 해면상 혈관종 환자를 보고하고자 한다. 선행 연구문헌의 요약: 뼈에 침습이 없는 경막외 해면상 혈관종은 매우 드문 질환으로 제한된 문헌 보고만이 존재한다. 대상 및 방법: 53세 여자 환자가 내원 한달여 전부터 시작된 좌측 하지의 감각저하를 동반한 저린 느낌을 주소로 내원하였다. 내원시 시행한 신경학적 검진에서 기타 다른 신경학적 이상 소견은 관찰되지 않았다. 자기공명영상에서는 흉추 11-12번간 좌측 추간공에 $2{\times}0.5cm$ 크기의 종괴가 관찰되었다. 수술을 시행하여 이를 완전 적출하였다. 결과: 병리 검사에서 해면상 혈관종이 확진되었다. 수술 부위의 약한 통증을 제외하고, 추적 관찰 2년동안 추가적인 신경학적인 증상 발생 없이 좋은 결과를 보였다. 수술 후 2년째에 촬영한 MRI에서 종양의 재발 소견은 관찰되지 않았다. 결론: 척추의 경막외 해면상 혈관종은 매우 드문 질환이며, 다른 경막외 병변들과 감별하기는 쉽지 않다. 그러나, 수술적 치료의 좋은 예후를 보이는 점을 감안하면, 경막외 병변의 감별진단시 이를 반드시 고려해야 할 것으로 생각한다.

Keywords

References

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