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어깨 통증을 주증상으로 내원한 경부 해면상 림프관종 1례

A case of cavernous lymphangioma causing shoulder pain

  • 박지훈 (한림대학교 강남성심병원 이비인후과학교실) ;
  • 이범상 (한림대학교 강남성심병원 이비인후과학교실) ;
  • 이종규 (한림대학교 강남성심병원 이비인후과학교실) ;
  • 장수경 (한림대학교 강남성심병원 이비인후과학교실) ;
  • 김진환 (한림대학교 강남성심병원 이비인후과학교실) ;
  • 김정원 (한림대학교 강남성심병원 병리학교실) ;
  • 이동진 (한림대학교 강남성심병원 이비인후과학교실)
  • Park, Ji Hoon (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Lee, Bum Sang (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Lee, Jong Kyu (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Jang, Soo Kyung (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Kim, Jin Hwan (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Kim, Jung Won (Department of Pathology, Kangnam Sacred Heart Hospital, Hallym University College of Medicine) ;
  • Lee, Dong Jin (Department of Otolaryngology-Head and Neck surgery, Kangnam Sacred Heart Hospital, Hallym University College of Medicine)
  • 투고 : 2018.09.03
  • 심사 : 2018.10.18
  • 발행 : 2018.11.30

초록

Cavernous lymphangioma is a rare congenital malformation that usually appears in the early childhood. The most common site is head and neck area, where approximately 75% of all lymphangiomas occur. We present a cavernous lymphangioma abutting brachial plexus and causing shoulder pain. A 28-year-old male patient presented with right shoulder pain for 2 months. Neck MRI revealed a lobulated multiseptated cystic mass at the anterior superior aspect of the right neck. Inferior, medial aspect of the mass was abutting brachial plexus. Surgical excision was performed, and pathologic result with immunohistochemical analysis confirmed the diagnosis cavernous lymphangioma.

키워드

참고문헌

  1. Mandel L. Parotid area lymphangioma in an adult: case report. J Oral Maxillofac Surg. 2004;62:1320-1323. https://doi.org/10.1016/j.joms.2003.12.040
  2. Shahi M, Bagga PK, Mahajan NC. Cervical cystic lymphangioma in an adult, diagnosed on FNAC. J Cytol. 2009;26:164-165. https://doi.org/10.4103/0970-9371.62191
  3. Ozturk A, Yousem DM. Magnetic resonance imaging findings in diffuse lymphangiomatosis: neuroradiological manifestations. Acta Radiol. 2007;48:560-564. https://doi.org/10.1080/02841850701352038
  4. Izumi D, Toyama E, Shigaki H, Iwagami S, Baba Y, Hayashi N, et al. Laparoscopic excision of an adult retroperitoneal cystic lymphangioma coexisting with an esophageal hiatus hernia. Clin J Gastroenterol. 2015;8:130-133. https://doi.org/10.1007/s12328-015-0571-1
  5. Chung JC, Song OP. Cystic lymphangioma of the jejunal mesentery presenting with acute abdomen in an adult. Can J Surg. 2009;52:E286-288.
  6. Pannell TL, Jolles H. Adult cystic mediastinal lymphangioma simulating a thymic cyst. J Thorac Imaging. 1991;7:86-89. https://doi.org/10.1097/00005382-199112000-00012
  7. Goodman J, Mc CJ, Denton GR, Stein A. Cystic hygromas in adults. Arch Surg. 1963;86:641-644. https://doi.org/10.1001/archsurg.1963.01310100125019
  8. Poyraz AS, Kilic D, Hatipoglu A, Ozulku M, Sar A, Bilezikci B. Cystic lymphangioma confined to mediastinum in an adult. Jpn J Thorac Cardiovasc Surg. 2004;52:567-569. https://doi.org/10.1007/s11748-004-0024-0
  9. Zanotti SD, LaRusso S, Coulson C. Prenatal sonographic diagnosis of axillary cystic lymphangiomas. J Clin Ultrasound. 2001;29:112-115. https://doi.org/10.1002/1097-0096(200102)29:2<112::AID-JCU1009>3.0.CO;2-Q
  10. Aneeshkumar MK, Kale S, Kabbani M, David VC. Cystic lymphangioma in adults: can trauma be the trigger? Eur Arch Otorhinolaryngol. 2005;262:335-337. https://doi.org/10.1007/s00405-004-0780-6
  11. Damaskos C, Garmpis N, Manousi M, Garmpi A, Margonis GA, Spartalis E, et al. Cystic hygroma of the neck: single center experience and literature review. Eur Rev Med Pharmacol Sci. 2017;21:4918-4923.
  12. Morley SE, Ramesar KC, Macleod DA. Cystic hygroma in an adult: a case report. J R Coll Surg Edinb. 1999;44:57-58.
  13. Allen CM. Radiology and oral and maxillofacial pathology. Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 1995;80:495.
  14. Kennedy TL. Cystic hygroma-lymphangioma: a rare and still unclear entity. Laryngoscope. 1989;99:1-10.
  15. Fung K, Poenaru D, Soboleski DA, Kamal IM. Impact of magnetic resonance imaging on the surgical management of cystic hygromas. J Pediatr Surg. 1998;33:839-841. https://doi.org/10.1016/S0022-3468(98)90654-6