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GENERALIZED HYPERCEMENTOSIS WITH ARRESTED DENTAL ERUPTION IN A CEREBRAL PALSY PATIENT : A CASE REPORT

뇌성마비 환자의 지연맹출을 동반한 다발성 과백악질증 : 증례보고

  • Kim, Byurira (Department of Pediatric Dentistry, College of Dentistry, Yonsei University) ;
  • Sun, Yeji (Department of Pediatric Dentistry, College of Dentistry, Yonsei University) ;
  • Song, Je Seon (Department of Pediatric Dentistry, College of Dentistry, Yonsei University) ;
  • Lee, Jae-ho (Department of Pediatric Dentistry, College of Dentistry, Yonsei University)
  • 김별이라 (연세대학교 치과대학 소아치과학교실) ;
  • 선예지 (연세대학교 치과대학 소아치과학교실) ;
  • 송제선 (연세대학교 치과대학 소아치과학교실) ;
  • 이제호 (연세대학교 치과대학 소아치과학교실)
  • Received : 2017.06.08
  • Accepted : 2017.08.09
  • Published : 2017.12.30

Abstract

Hypercementosis is an excessive deposition of secondary cementum on the root of a tooth. It is mostly presented as a solitary lesion or in rare cases as a generalized type, but which is seldom recognized; typically it is discovered during regular dental X-ray. Increased thickness of cementum is not uncommon but generalized hypercementosis on impacted permanent teeth which may cause delayed eruption is rarely reported. This case report discusses a patient with cerebral palsy, epilepsy and mental retardation that presents multiple hypercementosis with delayed eruption. On intraoral examination, multiple retained primary molar teeth were found. As there was no any further symptoms, regular dental checkup had been done for several years. In 2015, a surgical opening was performed in the second molar area, but there was no specific change. Panoramic view showed multiple impacted permanent teeth with increased thickness of roots due to excessive deposition of cementum. Hypercementosis was also observed in the root of the erupted tooth. Several laboratory test results including hormone, urine, complete blood count test were reviewed. The patient was also diagnosed with subclinical hypothyroidism, impaired fasting glucose and had been taken valproic acid($Orfil^{(R)}$) for 10 years. However, none of them clearly explained generalized hypercementosis or delayed eruption. The patient is now 24 years old and regular dental checkups and radiographs are taken to confirm that there is no change in the lesion.

본 증례는 다발성 과백악질증 및 영구치의 맹출 지연을 나타내는 뇌성마비 병력 환자에 대해 보고이다. 현재 환자는 큰 불편감 없이 유구치를 유지하고 있으며 방사선 사진 검사를 통해 매복 영구치의 낭종 발생 여부를 확인하고 잔존 유치를 최대한 보존해야 한다.

Keywords

References

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