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Tracheal Agenesis Reconstruction with External Esophageal Stenting: Postoperative Results and Complications

  • Park, Byung-Jo (Department of Thoracic and Cardiovascular Surgery, Samsung Medical Center, Sungkyunkwan University School of Medicine) ;
  • Kim, Min Soo (Department of Thoracic and Cardiovascular Surgery, Samsung Medical Center, Sungkyunkwan University School of Medicine) ;
  • Yang, Ji-Hyuk (Department of Thoracic and Cardiovascular Surgery, Samsung Medical Center, Sungkyunkwan University School of Medicine) ;
  • Jun, Tae-Gook (Department of Thoracic and Cardiovascular Surgery, Samsung Medical Center, Sungkyunkwan University School of Medicine)
  • Received : 2014.11.09
  • Accepted : 2014.11.25
  • Published : 2015.12.05

Abstract

Tracheal agenesis is an extremely rare and typically lethal congenital disorder. Approximately 150 cases have been described since 1900, and very few cases of survival have been reported. We describe tracheal reconstruction with external esophageal stenting in a patient with Floyd's type II tracheal agenesis. Neither long-term survival nor survival without mechanical ventilation for even a single day has previously been reported in patients with Floyd's type II tracheal agenesis. The infant in the present case survived for almost a year and breathed without a ventilator for approximately 50 days after airway reconstruction using external supportive stents.

Keywords

References

  1. Payne WA. Congenital absence of the trachea. Brooklyn Medical Journal 1900;14:568.
  2. Holinger PH, Johnston KC, Parchet VN. Congenital malformations of the trachea, bronchi and lung. Ann Otol Rhinol Laryngol 1952;61:1159-80. https://doi.org/10.1177/000348945206100419
  3. Floyd J, Campbell DC, Dominy DE. Agenesis of the trachea. Am Rev Respir Dis 1962;86:557-60.
  4. Koltai PJ, Quiney R. Tracheal agenesis. Ann Otol Rhinol Laryngol 1992;101:560-6. https://doi.org/10.1177/000348949210100704
  5. De Groot-van der Mooren MD, Haak MC, Lakeman P, et al. Tracheal agenesis: approach towards this severe diagnosis. Case report and review of the literature. Eur J Pediatr 2012; 171:425-31. https://doi.org/10.1007/s00431-011-1563-x
  6. Haben CM, Rappaport JM, Clarke KD. Tracheal agenesis. J Am Coll Surg 2002;194:217-22. https://doi.org/10.1016/S1072-7515(01)01157-7
  7. Shankar Raman V, Sugandhi N, Bhatnagar V. Role of the esophagus in surgery for tracheal agenesis. Eur J Pediatr Surg 2011;21:198-200. https://doi.org/10.1055/s-0031-1271736
  8. Usui N, Kamiyama M, Tani G, et al. Three-stage reconstruction of the airway and alimentary tract in a case of tracheal agenesis. Ann Thorac Surg 2010;89:2019-22. https://doi.org/10.1016/j.athoracsur.2009.11.021
  9. Watanabe T, Okuyama H, Kubota A, et al. A case of tracheal agenesis surviving without mechanical ventilation after external esophageal stenting. J Pediatr Surg 2008;43: 1906-8. https://doi.org/10.1016/j.jpedsurg.2008.06.013

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