Pediatric Gastroenterology, Hepatology & Nutrition

The Korean Society of Pediatric Gastroenterology, Hepatology and Nutrition (대한소아소화기영양학회)
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A Case of Cecal Volvulus Presenting with Chronic Constipation in Lissencephaly

  • Lee, Eun-Kyung (Department of Pediatrics, Yeungnam University Medical Center) ;
  • Kim, Ji Eun (Department of Pediatrics, Yeungnam University Medical Center) ;
  • Lee, Yun-Young (Department of Pediatrics, Yeungnam University Medical Center) ;
  • Kim, Saeyoon (Department of Pediatrics, Yeungnam University Medical Center) ;
  • Choi, Kwang Hea (Department of Pediatrics, Yeungnam University Medical Center)
  • Received : 2013.05.28
  • Accepted : 2013.06.21
  • Published : 2013.06.30
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Abstract

Cecal volvulus is uncommon in pediatric patients and there are few reports of cecal volvulus with cerebral palsy. Here, we report the case of a 19-year-old male patient who presented with abdominal distension, a history of cerebral palsy, refractory epilepsy due to lissencephaly, and chronic constipation. An abdominal x-ray and computed tomography without contrast enhancement showed fixed dilated bowel intensity in the right lower abdomen. Despite decompression with gastric and rectal tube insertion, symptoms did not improve. The patient underwent an exploratory laparotomy that revealed cecal volvulus. Cecal volvulus usually occurs following intestinal malrotation or previous surgery. In this patient, however, intestinal distension accompanying mental disability and chronic constipation resulted in the development of cecal volvulus. We suggest that cecal and proximal large bowel volvulus should be considered in patients presenting with progressive abdominal distension combined with a history of neuro-developmental delay and constipation.

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References

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  1. A Rare Case of Cecal Bascule in a Child With Normal Neurodevelopment : vol.36, pp.3, 2013, https://doi.org/10.1097/pec.0000000000001309