Tuberculosis and Respiratory Diseases

The Korean Academy of Tuberculosis and Respiratory Diseases (대한결핵및호흡기학회)
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A Case of Congenital Cystic Adenomatoid Malformation Infected with Mycobacterium avium-intracellulare Complex

  • Kim, Yong Jin (Department of Internal Medicine, Konkuk University School of Medicine) ;
  • Kim, Do Young (Department of Internal Medicine, Konkuk University School of Medicine) ;
  • Seo, Jung Woong (Department of Internal Medicine, Konkuk University School of Medicine) ;
  • Lee, Song Am (Department of Thoracic and Cardiovascular Surgery, Konkuk University School of Medicine) ;
  • Hwang, Jae Joon (Department of Thoracic and Cardiovascular Surgery, Konkuk University School of Medicine) ;
  • Kim, Hee Joung (Department of Internal Medicine, Konkuk University School of Medicine) ;
  • Lee, Kye Young (Department of Internal Medicine, Konkuk University School of Medicine)
  • Received : 2012.06.27
  • Accepted : 2012.07.16
  • Published : 2013.01.30
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Abstract

We present a case of congenital cystic adenomatoid malformation (CCAM) in a 25-year-old male who was presented with chronic cough. Chest radiography revealed an abnormal mass-like shadow in the right lower pulmonary zone. A contrast enhanced computed tomography showed an 11 cm solid, cystic mixed mass on the right lower lobe. A right lower lobectomy was performed by video-assisted thoracoscopic surgery without complications. The gross specimen showed a massive cavitation with multiloculated cysts of varying size, consistent with CCAM, along with noticeable granulomatous inflammation. Non-tuberculosis mycobacteria were isolated from a bronchial wash specimen, and the resected tissue homogenates were positive for Mycobacterium avium-intracellulare complex by polymerase chain reaction.

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References

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