TREATMENT FOR IDIOPATHIC MULTIPLE DENTIGEROUS CYSTS: CASE REPORT

양악 편측에 발생한 다발성 함치성 낭종의 치험례

  • Kim, Ki-Baek (Department of Pediatric Dentistry, Chonnam National University School of Dentistry, Dental Research Institute and Second stage of BK21) ;
  • Kim, Seon-Mi (Department of Pediatric Dentistry, Chonnam National University School of Dentistry, Dental Research Institute and Second stage of BK21) ;
  • Yang, Kyu-Ho (Department of Pediatric Dentistry, Chonnam National University School of Dentistry, Dental Research Institute and Second stage of BK21) ;
  • Choi, Nam-Ki (Department of Pediatric Dentistry, Chonnam National University School of Dentistry, Dental Research Institute and Second stage of BK21)
  • 김기백 (전남대학교 치의학전문대학원 소아치과학교실, 치의학연구소, 2단계 BK21) ;
  • 김선미 (전남대학교 치의학전문대학원 소아치과학교실, 치의학연구소, 2단계 BK21) ;
  • 양규호 (전남대학교 치의학전문대학원 소아치과학교실, 치의학연구소, 2단계 BK21) ;
  • 최남기 (전남대학교 치의학전문대학원 소아치과학교실, 치의학연구소, 2단계 BK21)
  • Published : 2009.05.30

Abstract

Dentigerous cysts generally encompass the crown of an unerupted tooth. These cysts are usually solitary. They are the second most common odontogenic type of cysts following radicular cysts, and are frequently associated with impacted mandibular third molars or maxillary canines. Most multiple cysts found in the jaw are odontogenic keratocysts associated with the nevoid basal cell carcinoma syndrome, mucopolysaccharidoses and cleidocranial dysplasia. Although a single dentigerous cyst is well documented in the medical literature, including the prevalence, treatment and prognosis, multiple dentigerous cysts without any systemic symptoms is unusual. Furthermore, cases involving both the maxilla and mandible are especially rare. We present the case of an 11-year-old boy with nonsyndromic multiple dentigerous cysts associated with a mandibular second premolar and a maxillary canine. The treatment was conservative and included marsupialization and eruption guidance. Further follow up is planned to rule out additional problems and the possible identification of a syndrome.

함치성 낭종은 일반적으로 미맹출 치아의 치관을 포함하고 있는 형태로, 치아 법랑질과 이장 상피 사이에 액체가 축적되어 생긴 잔존 법랑 상피조직의 퇴행성 변화로 부터 생긴다. 치근단 낭 다음으로 가장 흔한 치성 낭종으로, 주로 단독으로 발생하고 하악 제 3대구치와 상악 소구치에 호발한다. 악골의 다발성 낭종은 주로 기저세포 모반 증후군과 관련된 치성 각화낭이 대부분이고, 점액다당류증 또는 쇄골두개 이형성증과도 관련이 있을 수 있다. 단발성의 함치성 낭종은 우리에게 친숙할 정도로 유병율에서 치료 및 예후까지 잘 알려져 있으나, 전신병력이 없는 다발성의 함치성 낭종은 드물며, 상악과 하악에 발생한 다발성 낭종은 특히 더 드물다. 본 증례는 편측성으로 양악에 함께 발생한 다발성의 함치성 낭종을 가진 11세 소년에 대한 치료 증례로 1년간의 관찰 후 양호할만한 결과를 얻었기에 보고하는 바이다. 1년이라는 관찰 기간이 짧기 때문에 향후 지속적인 임상적, 방사선적 관찰을 필요로 하리라 사료된다.

Keywords

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