Endobronchial Leiomyoma Combined with Pulmonary Sequestration -A case report -

폐격리증을 동반한 기관지 내 평활근종 -1예 보고-

  • Lee Seock-Yeol (Department of Thoracic and Cardiovascular Surgery, Soonchunyang University College of Medicine) ;
  • Oh Jae-Yoon (Department of Thoracic and Cardiovascular Surgery, Soonchunyang University College of Medicine) ;
  • Lee Seung-Jin (Department of Thoracic and Cardiovascular Surgery, Soonchunyang University College of Medicine) ;
  • Lee Cheol-Sae (Department of Thoracic and Cardiovascular Surgery, Soonchunyang University College of Medicine) ;
  • Lee Kihl-Rho (Department of Thoracic and Cardiovascular Surgery, Soonchunyang University College of Medicine) ;
  • Cho Hyun-Deuk (Department of Anatomic Pathology, Soonchunyang University College of Medicine)
  • 이석열 (순천향대학교 의과대학 흉부외과학교실) ;
  • 오재윤 (순천향대학교 의과대학 흉부외과학교실) ;
  • 이승진 (순천향대학교 의과대학 흉부외과학교실) ;
  • 이철세 (순천향대학교 의과대학 흉부외과학교실) ;
  • 이길노 (순천향대학교 의과대학 흉부외과학교실) ;
  • 조현득 (순천향대학교 의과대학 해부병리학교실)
  • Published : 2006.07.01

Abstract

A 42-year-old female was admitted to our hospital complaining of a dyspnea. Chest X-ray showed left atelectasis. A mass was detected in left main bronchus by computed tomography and bronchoscopy. The mass was diagnosed as a endobronchial leiomyoma by biopsy exam. After open thoracotomy and bronchotomy, mass removal was done and middle lobe was ventilated normally. Aberrant arterial supply from descending aorta to left lower lobe of the lung was detected and left lower lobectomy was done. The lower lobe of the left lung was pathologically diagnosed as intralobar pulmonary sequestration. Herein we report a rare coexistent case of endobronchial leiomyoma and intralobar pulmonary sequestration.

호흡곤란을 주소로 내원한 42세 여자환자가 단순 흉부 촬영상 좌측 폐의 무기폐 소견을 보였다. 기관지 내시경과 흉부 컴퓨터 단층촬영상 좌측 주기관지에 종괴가 발견되었다. 조직검사상 종괴는 기관지 평활근종으로 진단되었다. 개흉술을 실시하여 좌측 주기관지절개를 하고 종괴를 제거하자 중엽은 정상적으로 환기가 되었다. 또한 하행대동맥에서 좌폐하엽으로 공급되는 이상동맥이 발견되어 좌폐하엽 절제수술을 동시에 실시하였다. 병리검사상 좌폐하엽은 내엽형 폐격리증으로 진단되었다. 저자들은 기관지 평활근종과 내엽형 폐격리증이 공존하는 드문 질환을 치험하였기에 보고하는 바이다.

Keywords

References

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